Periductal stromal sarcoma is a rare lesion. It was considered to be a variant of phyllode tumor whereas they are morphologically different. Our patient was a 39 years old, with no previous history, who presented a nodular formation at the level of the inferior-internal quadrant of the right breast operated in 2015 with the realization of a nodule excision. The histological examination carried out was in favor of the diagnosis of a periductal stromal sarcoma with tumoral surgical excision limits. 2 years later, she presented a recurrence at the level of the tumor scar. A bilateral digital mammography was performed which showed an appearance in favor of a tumor recurrence of 63 mm of major axis at the level of the inferior-internal quadrant of the right breast. She was given a biopsy excision communicated to our structure. The diagnosis of the recurrence of a periuctal stromal sarcoma has been retained. The number of studies available on periductal stromal sarcoma (SPP/PSS) is currently limited and a therapeutic strategy for the PSS has not yet been determined. The histological diagnosis of PSS is based on the criteria established by the AFIP, and surgery with significant margins is the cornerstone of treatment.